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Resection of a cardiac aneurysm in an infant with anomalous origin of the left coronary artery from the pulmonary trunk

Published online by Cambridge University Press:  20 January 2005

Heynric B. Grotenhuis ,
Ad Backx  and
Aagje Nijveld
Heynric B. Grotenhuis
Affiliation:
Department of Pediatric Intensive Care, University Hospital Nijmegen, Nijmegen, The Netherlands
Ad Backx
Affiliation:
Department of Pediatric Intensive Care, University Hospital Nijmegen, Nijmegen, The Netherlands
Aagje Nijveld
Affiliation:
Department of Pediatric Intensive Care, University Hospital Nijmegen, Nijmegen, The Netherlands
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Abstract

We describe an infant with an anomalous left coronary artery arising from the pulmonary trunk leading to myocardial ischaemia and development of an apical aneurysm of the left ventricle.

Clinical presentation in general is based on myocardial hypoperfusion resulting in ischaemia and infarction. When presenting in infancy, however, then the features, as in our patient, may be tachypnea, dyspnea, failure to thrive and irritability, especially during feeding. Then, again as in our patient, it is possible to miss the definitive diagnosis, which is made by echocardiography and cardiac catheterization. Reimplantation of the anomalous left coronary artery into the aorta usually results in improvement of left ventricular function over time. In our patient, the myocardial infarction was complicated by formation of an aneurysm, and reimplantation alone was not sufficient to restore cardiac function. Resection of the aneurysm greatly improved the hemodynamics.

Keywords

ALCAPABland-White-Garland syndromeinfancycardiac aneurysm
Type
Brief Report
Information
Cardiology in the Young , Volume 14 , Issue 1 , February 2004 , pp. 106 - 108
Copyright
© 2004 Cambridge University Press

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