Hostname: page-component-586b7cd67f-vdxz6 Total loading time: 0 Render date: 2024-11-26T03:30:55.933Z Has data issue: false hasContentIssue false
  • English
  • Français

Rapid recurrence of an inflammatory myofibroblastic tumor in the right ventricular outflow tract

Published online by Cambridge University Press:  19 August 2008

István L. Hartyánszky ,
Krisztina Kádár  and
Márta Hubay
István L. Hartyánszky*
Affiliation:
Hungarian Institute of cardiology, Budapest, Hungary
Krisztina Kádár
Affiliation:
Hungarian Institute of cardiology, Budapest, Hungary
Márta Hubay
Affiliation:
Semmelweis School of Medicine, Department of Forensic Medicine, Budapest, Hungary
*
Prof.István L.Hartyánszky MD.PhD, Hungarian Institute of Cardiology, Paediatric Cardiac Surgery Department, 1096 Budapest Halleru.29.Hungary. Tel: (1) 2151–220; Fax: (1) 2157–067; E-mail: [email protected]
Get access Rights & Permissions [Opens in a new window]

Abstract

We describe an unusual case of rapid recurrence of a previously excised inflammatory myofibroblastic tumor of the right ventricular outflow tract in a 5-month-old infant. The infant is asymptomatic 18 months after the second surgery. The very rare cardiac involvement, and the early relapse of the inflammatory pseudotumor, to the best of our knowledge, is a unique combination.

The inflammatory myofibroblastic tumor, as known as a pseudotumor or plasma cell granuloma is an uncommon reactive lesion with unknown aetiology. It is found most commonly in the lung and a number of visceral organs, such as the spleen, liver, ileum, salivary glands, urinary bladder, larynx or brain or in the retroperitoneum and lymph nodes. To our knowledge only 9 cases have been published of such tumor arising within the heart.1–6

Keywords

Cardiac inflammatory myofibroblastic tumorinflammatory pseudotumorpaediatric cardiology
Type
Brief Reports
Information
Cardiology in the Young , Volume 10 , Issue 3 , May 2000 , pp. 271 - 274
Copyright
Copyright © Cambridge University Press 2000

Access options

Get access to the full version of this content by using one of the access options below. (Log in options will check for institutional or personal access. Content may require purchase if you do not have access.)

References

1.Conzales-Crussi, F., Vanderbilt, B., Miller, J. Unusual intracardiac tumor in a child. Cancer 1975; 36: 2214–2226.CrossRefGoogle Scholar
2.Pearson, P, Smithson, W, Driscoll, D, Banks, P, Ehman, R. Inoperable plasma cell granuloma of the heart: spontaneous decrease in size during an 11-month period. Mayo Clin Proc 1988; 63:1022–1025.CrossRefGoogle ScholarPubMed
3.Stark, P, Sandbank, JC, Rudnicki, C, Zahavi, I. Inflammatory pseudotumor of the heart with vasculitis and venous throm bosis. Chest 1992; 102:1884–1885.CrossRefGoogle Scholar
4.Coffin, CM, Watterson, J, Priest, JR, Dehner, LP. Extrapulmonary inflammatory myofibroblastic tumor (inflammatory pseudotumor). A clinicopathologic and immunohistochemical study of 84 cases. Am J Surg Pathol 1995;19(8):859–872.CrossRefGoogle ScholarPubMed
5.Rose, AG, McCormick, S, Cooper, K, Titus, JL. Inflammatory pseudotumor (plasma cell granuloma) of the heart. Report of two cases and literature review. Arch Pathol Lab Med 1996; 120: 549–554.Google ScholarPubMed
6.Jenkins, PC, Dickinson, AE, Flanagan, MF. Cardiac inflammatory pseudotumor: rapid appearance in an infant with congenital heart disease. Pediatr Cardiol 1996; 17:399–401.CrossRefGoogle Scholar