Hostname: page-component-586b7cd67f-2plfb Total loading time: 0 Render date: 2024-11-26T12:58:12.383Z Has data issue: false hasContentIssue false

Single right coronary artery with right ventricular fistula and congenital absence of left coronary artery: an extremely rare combination

Published online by Cambridge University Press:  05 September 2019

Tamer Yoldaş*
Affiliation:
Department of Pediatric Cardiology, Dr. Sami Ulus Maternity, Children’s Health and Diseases Training and Research Hospital, Ankara, Turkey
Meryem Beyazal
Affiliation:
Department of Pediatric Cardiology, Dr. Sami Ulus Maternity, Children’s Health and Diseases Training and Research Hospital, Ankara, Turkey
Utku A. Örün
Affiliation:
Department of Pediatric Cardiology, Dr. Sami Ulus Maternity, Children’s Health and Diseases Training and Research Hospital, Ankara, Turkey
*
Author for correspondence: T. Yoldaş, MD, Department of Cardiology, Dr. Sami Ulus Maternity, Children’s Health and Diseases Training and Research Hospital, Babür Caddesi Number: 44 (06080) Altındağ, Ankara, Turkey. Tel: +90 (312) 305 6570; Fax: +90 (312) 317 03 53, E-mail: [email protected]

Abstract

We report an extremely rare case of a 14-month-old girl who was diagnosed with a single right coronary artery with coronary artery fistula communicating with the right ventricle and congenital absence of left coronary artery. Angiography showed a dilated and tortuous single right coronary artery draining into the right ventricle, absence of left coronary system, and left ventricular coronary circulation supplied via collateral vessels.

Type
Brief Report
Copyright
© Cambridge University Press 2019 

Access options

Get access to the full version of this content by using one of the access options below. (Log in options will check for institutional or personal access. Content may require purchase if you do not have access.)

References

Ishii, Y, Suzuki, T, Kobayashi, T, Arakawa, H. Single coronary artery with right ventricular fistula: case report and literature review. Congenital Heart Dis 2010; 5: 5659.10.1111/j.1747-0803.2009.00308.xCrossRefGoogle ScholarPubMed
Sunder, KR, Balakrishnan, KG, Tharakan, JA, et al. Coronary artery fistula in children and adults: a review of 25 cases with long-term observations. Int J Cardiol 1997; 58: 4753.10.1016/S0167-5273(96)02792-1CrossRefGoogle ScholarPubMed
Shirani, J, Roberts, WC. Solitary coronary ostium in the aorta in the absence of other major congenital cardiovascular anomalies. J Am Coll Cardiol 1993; 21: 137–43.10.1016/0735-1097(93)90728-JCrossRefGoogle ScholarPubMed
Fu, F, Jin, H, Feng, Y. A rare case of single right coronary artery with congenital absence of left coronary artery in an adult: a case report. J Cardiothorac Surg 2015; 10: 57.10.1186/s13019-015-0267-0CrossRefGoogle Scholar
Siddiqui, SM, Rao, RCK, Kaza, S, Kumar, EAP. Computed tomography coronary angiography diagnosis of single right coronary artery with congenital absence of left coronary artery system equivalents. Indian J Radiol Imaging 2016; 26(2): 198200.Google ScholarPubMed
Smith, JC. Review of single coronary artery with report of 2 cases. Circulation 1950; 1: 11681175.10.1161/01.CIR.1.5.1168CrossRefGoogle ScholarPubMed
Lipton, MJ, Barry, WH, Obrez, I, Silverman, JF, Wexler, L. Isolated single coronary artery: diagnosis, angiographic classification, and clinical significance. Radiology 1979; 130: 3947.CrossRefGoogle ScholarPubMed
Qureshi, SA. Coronary arterial fistulas. Orphanet J Rare Diseases 2006; 1: 51. CrossRefGoogle ScholarPubMed