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Life saved and a lesson learned-anomalous origin of the left coronary artery from pulmonary artery in pregnancy

Published online by Cambridge University Press:  31 August 2021

Salima A. Bhimani*
Affiliation:
Department of Pediatric Cardiology, Cleveland Clinic Children’s, Cleveland, OH, USA
Hani K. Najm
Affiliation:
Department of Pediatric and Congenital Heart Surgery, Heart and Vascular Institute, Cleveland Clinic, Cleveland, OH, USA
Rukmini Komarlu
Affiliation:
Department of Pediatric Cardiology, Cleveland Clinic Children’s, Cleveland, OH, USA
*
Author for correspondence: S. A. Bhimani, Pediatric Cardiology Department, Desk M41, 9500 Euclid Avenue, Cleveland, OH 44195, USA. Tel: +1 352-870-9135; Fax: +1 216-445-5679. E-mail: [email protected]

Abstract

Anomalous origin of the left coronary artery from pulmonary artery constitutes 0.5% of all CHD (Boutsikou M, Shore D, Li W, et al, Int J Cardiol 261: 49–53, 2018). Fifteen percent survive into adulthood undiagnosed and 90% present with sudden death (Yau JM, Singh R, Halpern EJ, Fischman D, Clin Cardiol 34: 204–210, 2011; Alexi-Meskishvili V, Berger F, Weng Y, Lange PE, Hetzer R, J Card Surg 10: 309–315, 1995). We describe an enigmatic case of a 29-year-old female who presented after an aborted cardiac arrest and was diagnosed with anomalous origin of the left coronary artery from pulmonary artery.

Type
Brief Report
Copyright
© The Author(s), 2021. Published by Cambridge University Press

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Footnotes

Oral Presentation at the 23rd Annual Scientific Sessions of the Society of Cardiovascular Magnetic Resonance, Orlando, 13 February, 2020.

References

Boutsikou, M, Shore, D, Li, W, et al. Anomalous left coronary artery from the pulmonary artery (ALCAPA) diagnosed in adulthood: varied clinical presentation, therapeutic approach and outcome. Int J Cardiol 2018; 261: 4953.CrossRefGoogle ScholarPubMed
Yau, JM, Singh, R, Halpern, EJ, Fischman, D. Anomalous origin of the left coronary artery from the pulmonary artery in adults: a comprehensive review of 151 adult cases and a new diagnosis in a 53-year-old woman. Clin Cardiol 2011; 34: 204210. DOI 10.1002/clc.20848.CrossRefGoogle Scholar
Alexi-Meskishvili, V, Berger, F, Weng, Y, Lange, PE, Hetzer, R. Anomalous origin of the left coronary artery from the pulmonary artery in adults. J Card Surg 1995; 10: 309315.CrossRefGoogle ScholarPubMed
Chattranukulchai, P, Namchaisiri, J, Tumkosit, M, et al. Very late presentation of anomalous origin of the left coronary artery from the pulmonary artery: case report. J Cardiothorac Surg 2018; 13: 70 (1–4 pages).10.1186/s13019-018-0751-4CrossRefGoogle ScholarPubMed
Peña, E, Nguyen, ET, Merchant, N, Dennie, C. ALCAPA syndrome: not just a pediatric disease. Radiographics 2009; 29: 553565.CrossRefGoogle Scholar
Qiu, QY, Yang, JX, Wang, XX. Anomalous origin of the left coronary artery from the pulmonary artery in a patient of advanced age: a case report and analysis. J Int Med Res 2019; 47: 26872693.CrossRefGoogle Scholar
Dilaveris, P, Koutagiar, I, Alexopoulos, N, Tsiachris, D, Gatzoulis, K. Secondary prevention of sudden cardiac death in a 65 year untreated ALCAPA patient. Int J Cardiol 2014; 176: e73e74.CrossRefGoogle Scholar
Soma-Pillay, P, Nelson-Piercy, C, Tolppanen, H, Mebazaa, A. Physiological changes in pregnancy. Cardiovasc J Afr 2016; 27: 8994.CrossRefGoogle ScholarPubMed
Kim, BG, Cho, SW, Hwang, DH, Nah, JC. Multimodality imaging of anomalous left coronary artery from the pulmonary artery. J Cardiovasc Ultrasound 2017; 25: 107109.CrossRefGoogle ScholarPubMed
Stout, KK, Daniels, CJ, Aboulhosn, JA, et al. 2018 AHA/ACC guideline for the management of adults with congenital heart disease: a report of the American College of Cardiology/American Heart Association task force on clinical practice guidelines. J Am Coll Cardiol 2019; 73: e81e192.CrossRefGoogle Scholar