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Left bronchial compression and pulmonary hypertension related to anomalous right pulmonary artery

Published online by Cambridge University Press:  22 February 2016

Jennifer A. Su ,
Andrew L. Cheng  and
Jacqueline R. Szmuszkovicz
Jennifer A. Su*
Affiliation:
Department of Pediatrics, Division of Cardiology, Children’s Hospital of Los Angeles, Los Angeles, California, United States of America
Andrew L. Cheng
Affiliation:
Department of Pediatrics, Division of Cardiology, Children’s Hospital of Los Angeles, Los Angeles, California, United States of America
Jacqueline R. Szmuszkovicz
Affiliation:
Department of Pediatrics, Division of Cardiology, Children’s Hospital of Los Angeles, Los Angeles, California, United States of America
*
Correspondence to: J. A. Su, MD, Children’s Hospital of Los Angeles, 4650 W. Sunset Blvd, Mailstop #34, Los Angeles, CA 90027, United States of America. Tel: +323 361 8308; Fax: +323 361 1513; E-mail: [email protected]
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Abstract

Anomalous origin of a pulmonary artery from the ascending aorta is a congenital defect that can be complicated by pulmonary arterial hypertension, typically due to vascular disease if the anomaly is left uncorrected past 6 months of age. We describe a unique case of severe pulmonary arterial hypertension with this defect in a 1-month-old infant unexpectedly caused instead by bronchial compression from her dilated left pulmonary artery.

Keywords

Anomalous origin of one pulmonary artery from the aortaheart failureinfantpulmonary arterial hypertensionpulmonary vascular disease
Type
Brief Reports
Information
Cardiology in the Young , Volume 26 , Issue 5 , June 2016 , pp. 999 - 1001
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Copyright
© Cambridge University Press 2016 

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References

1. Kutsche, LM, Van Mierop, LH. Anomalous origin of a pulmonary artery from the ascending aorta: associated anomalies and pathogenesis. Am J Cardiol 1988; 61: 850–856.CrossRefGoogle ScholarPubMed
2. Fraentzel, O. Ein fall von abnormer communication der aorta mit der arteria pulmonalis. Arch Pathol Anat 1868; 43: 420–426.CrossRefGoogle Scholar
3. Keane, JF, Maltz, D, Bernhard, WF, Corwin, RD, Nadas, AS. Anomalous origin of one pulmonary artery from the ascending aorta. Diagnostic, physiological and surgical considerations. Circulation 1974; 50: 588–594.CrossRefGoogle ScholarPubMed
4. Nigam, A, Trehan, V, Agarwal, S. Bilateral pulmonary vein stenting through an unligated vertical vein in a postoperative case of TAPVC. J Card Surg 2014; 29: 705–708.CrossRefGoogle Scholar
5. Nathan, M, Rimmer, D, Piercey, G, et al. Early repair of hemitruncus: excellent early and late outcomes. J Thorac Cardiovasc Surg 2007; 133: 1329–1335.CrossRefGoogle ScholarPubMed
6. Robotin, MC, Bruniaux, J, Serraf, A, et al. Unusual forms of tracheobronchial compression in infants with congenital heart disease. J Thorac Cardiovasc Surg 1996; 112: 415–423.CrossRefGoogle ScholarPubMed
7. Kussman, BD, Geva, T, McGowan, FX. Cardiovascular causes of airway compression. Paediatr Anaesth 2004; 14: 60–74.CrossRefGoogle ScholarPubMed
8. Park, SH, Park, SY, Kim, NK, et al. Bronchial compression in an infant with isolated secundum atrial septal defect associated with severe pulmonary arterial hypertension. Korean J Pediatr 2012; 55: 297–300.CrossRefGoogle Scholar
9. Ben-Shachar, G, Beder, SD, Liebman, J, Van Heeckeren, D. Hemitruncal sling: a newly recognized anomaly and its surgical correction. J Thorac Cardiovasc Surg 1985; 90: 146–148.CrossRefGoogle ScholarPubMed
10. Rosa, U, Wade, KC. Bronchoscopic findings in hemitruncus. Thorax 1988; 43: 214–215.CrossRefGoogle ScholarPubMed